Vol 70, No 5 (2020)
Case report
Published online: 2020-10-05

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A rare complex variant translocation t(9;22;6;17;1) in chronic myeloid leukemia: case report

Agnieszka Chudy1, Barbara Pieńkowska-Grela1, Aleksandra Kotyl1, Renata Woroniecka1, Jolanta Rygier1, Katarzyna Wojtkowska1, Ewa Wasińska2, Karolina Wąsowska3, Renata Chodurska3, Artur Kowalik3, Beata Grygalewicz1
Nowotwory. Journal of Oncology 2020;70(5):206-210.

Abstract

The presence of the Philadelphia chromosome (Ph) in chronic myelogenous leukaemia (CML) is a specific cytogenetic change resulting from a reciprocal translocation between chromosomes 9 and 22. In 5–10% of newly diagnosed cases there are variant translocations (vPh) involving more chromosomes. This paper presents the case of a CML patient with a complex variant translocation involving chromosomes 1, 6, 9, 17 and 22. A molecular analysis did not reveal any muta­tion in the kinase domain of BCR-ABL1 gene or the mutation of TP53 gene. After the first-line treatment with imatinib no cytogenetic or molecular response was obtained. The change of treatment to dasatinib resulted in a minimal cytogenetic response (minCyR) followed by a minor cytogenetic response (mCyR). The application of nilotinib in the third-line treatment resulted in a complete molecular response (CMolR) and therapy success. The likely reason for the failure of the first- and second-line treatment was the loss of a fragment of the 17p13 region as a result of a variant translocation. The change can be a functional equivalent of the loss of one copy of TP53. The analysis of presented case confirms the significance of the detailed evaluation of the composition of vPh complex variant translocations as well as importance of combination cytogenetic and molecular diagnostics in CML treatment monitoring. It makes possible to adequate diagnose higher-risk patients and apply effective treatment strategies if an aberration is identified.

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References

  1. Żołnierowicz J, Kawiak J, Hoser G. Patogeneza przewlekłej białaczki szpikowej — od genu do terapii celowanej. Hematologia. 2010; 1(3): 195–218.
  2. Jabbour E, Kantarjian H. Chronic myeloid leukemia: 2018 update on diagnosis, therapy and monitoring. Am J Hematol. 2018; 93(3): 442–459.
  3. Alhuraiji A, Kantarjian H, Boddu P, et al. Prognostic significance of additional chromosomal abnormalities at the time of diagnosis in patients with chronic myeloid leukemia treated with frontline tyrosine kinase inhibitors. Am J Hematol. 2018; 93(1): 84–90.
  4. Caren H. Cytogenetics of Chronic Myelogenous Leukemia. US Pharm. 2008; 33(7 Oncology suppl): 14–22.
  5. Wang W, Cortes JE, Tang G, et al. Risk stratification of chromosomal abnormalities in chronic myelogenous leukemia in the era of tyrosine kinase inhibitor therapy. Blood. 2016; 127(22): 2742–2750.
  6. Hochhaus A, Baccarani M, Silver RT, et al. European LeukemiaNet 2020 recommendations for treating chronic myeloid leukemia. Leukemia. 2020; 34(4): 966–984.
  7. Hellmann A. VI.F Przewlekła białaczka szpikowa. In: Gajewski P. ed. Interna Szczeklika: podręcznik chorób wewnętrznych. Medycyna Praktyczna, Kraków 2018: 1771.
  8. Sasaki K, Strom SS, O'Brien S, et al. Relative survival in patients with chronic-phase chronic myeloid leukaemia in the tyrosine-kinase inhibitor era: analysis of patient data from six prospective clinical trials. Lancet Haematol. 2015; 2(5): e186–e193.
  9. Sacha T, Foryciarz K. Diagnostyka i ocena skuteczności leczenia przewlekłej białaczki szpikowej. Hematologia. 2010; 1(3): 219–228.
  10. Cohen N, Rozenfeld-Granot G, Hardan I, et al. Subgroup of patients with Philadelphia-positive chronic myelogenous leukemia characterized by a deletion of 9q proximal to ABL gene: expression profiling, resistance to interferon therapy, and poor prognosis. Cancer Genet Cytogenet. 2001; 128(2): 114–119.
  11. Allen-Proctor K, Ruckdeschel E, Naous R. A novel three-way Philadelphia Variant t(9;22;17)(q34;q11.2;q12) in chronic myeloid leukemia: A case report. Mol Clin Oncol. 2018; 8(2): 300–301.
  12. Wendel HG, de Stanchina E, Cepero E, et al. Loss of p53 impedes the antileukemic response to BCR-ABL inhibition. Proc Natl Acad Sci U S A. 2006; 103(19): 7444–7449.
  13. Kokate P, Dalvi R, Mandava S. A complex three-way translocation with deletion of the TP53 gene in a blast crisis chronic myeloid leukemia patient. J Cancer Res Ther. 2015; 11(4): 1037.
  14. Studniak E, Zajączek S. Rola genu P53 i delecji w obszarze 17p w powstawaniu i przebiegu białaczek i zespołów mielodysplastycznych. Acta Haematol Pol. 2011; 42(4): 629–638.
  15. Bennour A, Saad A, Sennana H. Chronic myeloid leukemia: Relevance of cytogenetic and molecular assays. Critical Reviews in Oncology/Hematology. 2016; 97: 263–274.
  16. Marzocchi G, Castagnetti F, Luatti S, et al. Gruppo Italiano Malattie EMatologiche dell'Adulto (GIMEMA) Working Party on Chronic Myeloid Leukemia. Variant Philadelphia translocations: molecular-cytogenetic characterization and prognostic influence on frontline imatinib therapy, a GIMEMA Working Party on CML analysis. Blood. 2011; 117(25): 6793–6800.
  17. Weisberg E, Manley P, Mestan J, et al. AMN107 (nilotinib): a novel and selective inhibitor of BCR-ABL. Br J Cancer Suppl. 2006; 94(12): 1765–1769.
  18. de Almeida Filho TP, Maia Filho PA, Barbosa MC, et al. Does BCR-ABL transcript type influence the prognosis of patients in chronic myelogenous leukemia chronic phase? Hematol Transfus Cell Ther. 2019; 41(2): 114–118.
  19. Pagnano KB, Miranda EC, Delamain MT, et al. Influence of BCR-ABL Transcript Type on Outcome in Patients With Chronic-Phase Chronic Myeloid Leukemia Treated With Imatinib. Clin Lymphoma Myeloma Leuk. 2017; 17(11): 728–733.
  20. Lipton JH, Bryden P, Sidhu MK, et al. Comparative efficacy of tyrosine kinase inhibitor treatments in the third-line setting, for chronic-phase chronic myelogenous leukemia after failure of second-generation tyrosine kinase inhibitors. Leuk Res. 2015; 39(1): 58–64.
  21. Al-Achkar W, Wafa A, Moassass F, et al. A novel dic (17;18) (p13.1;q11.2) with loss of TP53 and BCR/ABL rearrangement in an Imatinib resistant chronic myeloid leukemia. Mol Cytogenet. 2012; 5(1): 36.
  22. Al-Kuraishy HM, Al-Gareeb AI, Al-Buhadilly AK. p53 Gene (NY-CO-13) Levels in Patients with Chronic Myeloid Leukemia: The Role of Imatinib and Nilotinib. Diseases. 2018; 6(1).